TODENTJ-25-03-2019_TODENTJ-3-144 1553505074 Bentham Open doi@benthamopen.net Bentham Open The Open Dentistry Journal TODENTJ 1874-2106 6 29 2009 3 1 Fabrício Rezende do Amaral Vinicius Magalhães Carvalho Marina Guimarães Fraga Tânia Mara Pimenta Amaral Carolina Cavaliéri Gomes Ricardo Santiago Gomez The glycogen storage disease (GSD) is a group of inherited disorders that involve deficiencies in the enzymes that metabolize glycogen. The purpose of the present paper is to report a rare case of GSD type 1b that presented both peripheral and central giant cell granuloma, and to discuss the possible explanation for this unusual finding. The use of corticosteroids in the management of central giant cell granuloma is also demonstrated. 6 29 2009 144 146 TODENTJ-3-144 1 10.2174/crossmark_policy opendentistryjournal.com benthamopen.com true Peer Reviewed Single blind Checked with iThenticate 2009-2-13 2009-4-2 2009-5-8 2009-6-29 http://creativecommons.org/licenses/by-nc/3.0/ 10.2174/1874210600903010144 1553505074 https://opendentistryjournal.com/VOLUME/3/PAGE/144/ https://opendentistryjournal.com/contents/volumes/V3/TODENTJ-3-144/TODENTJ-3-144.pdf https://opendentistryjournal.com/contents/volumes/V3/TODENTJ-3-144/TODENTJ-3-144.pdf https://opendentistryjournal.com/contents/volumes/V3/TODENTJ-3-144/TODENTJ-3-144.pdf https://opendentistryjournal.com/contents/volumes/V3/TODENTJ-3-144/TODENTJ-3-144.pdf https://opendentistryjournal.com/contents/volumes/V3/TODENTJ-3-144/TODENTJ-3-144.pdf https://opendentistryjournal.com/contents/volumes/V3/TODENTJ-3-144/TODENTJ-3-144.pdf https://opendentistryjournal.com/contents/volumes/V3/TODENTJ-3-144/TODENTJ-3-144.pdf https://opendentistryjournal.com/contents/volumes/V3/TODENTJ-3-144/TODENTJ-3-144.xml Pediatr Dent Dougherty N 17 224 1995 Dougherty N, Gataletto MA. Oral sequelae of chronic neutrophil defects: case report of a child with glycogen storage disease type 1b Pediatr Dent 1995; 17 : 224-9. Transplant Proc Martin AP 38 3615 2006 Martin AP, Bartels M, Schreiber S, Buehrdel P, Hauss J, Fangmann J. Successful staged kidney and liver transplantation for glycogen storage disease type Ib: A case report Transplant Proc 2006; 38 : 3615-9. J Biol Chem Pan CJ 274 13865 1999 Pan CJ, Lin B, Chou JY. Transmembrane topology of human glucose 6-phosphate transporter J Biol Chem 1999; 274 : 13865-9. Pediatr Dent Katz J 19 123 1997 Katz J, Shenkman Z, Sela M, Rakotz M, Garty BZ. Oral manifestations and anesthesia considerations in a child with glycogen storage disease type 1b: case report Pediatr Dent 1997; 19 : 123-6. Braunwald E, Kurt J, Isselbacher KJ. Harrison’s principles of internal medicine. 11th. New York: McGraw-Hill 1987. World J Gastroenterol Ozen H 13 2541 2007 Ozen H. Glycogen storage disease: New perspectives World J Gastroenterol 2007; 13 : 2541-53. J Inherit Metab Dis Narisawa K 9 297 1986 Narisawa K, Ishizawa S, Okumura H, Tada K, Kuzuya T. Neutrophil metabolic dysfunction in genetically heterogeneous patients with glycogen storage disease type 1b J Inherit Metab Dis 1986; 9 : 297-300. Eur J Pediatr Bianchi L 152 S63 1993 Bianchi L. Glycogen storage disease I and hepatocellular tumors Eur J Pediatr 1993; 152 : S63-70. Oral Surg Oral Med Oral Pathol Barret AP 69 174 1990 Barret AP, Buckley DJ, Katelaris CH. Oral complications in type 1B glycogen storage disease Oral Surg Oral Med Oral Pathol 1990; 69 : 174-6. J Oral Pathol Med Salapata Y 24 136 1995 Salapata Y, Laskaris G, Drogari E, Harokopos E, Messaritakis J. Oral manifestations in glycogen storage disease type 1b J Oral Pathol Med 1995; 24 : 136-9. J Craniofac Surg Mortellaro C 16 45 2005 Mortellaro C, Garagiola U, Carbone V, Cerutti F, Marci V, Bonda PL. Unusual oral manifestations and evolution in glycogen storage disease type Ib J Craniofac Surg 2005; 16 : 45-52. Oral Surg Oral Med Oral Radiol Endod Carlos R 93 161 2002 Carlos R, Sedano HO. Intralesional corticosteroids as an alternative treatment for central giant cell granuloma Oral Surg Oral Med Oral Radiol Endod 2002; 93 : 161-6. Br J Oral Maxillofac Surg Abdo EN 43 74 2005 Abdo EN, Alves LC, Rodrigues AS, Mesquita RA, Gomez RS. Treatment of a central giant cell granuloma with intralesional corticosteroid Br J Oral Maxillofac Surg 2005; 43 : 74-6. Eur J Pediatr Visser G 161 S83 2002 Visser G, Rake JP, Labrune P, et al. Granulocyte colony-stimulating factor in glycogen storage disease type 1b. Results of the European study on glycogen storage disease type 1b Eur J Pediatr 2002; 161 : S83-7. J Clin Invest Kitaura H 115 3418 2005 Kitaura H, Zhou P, Kim HJ, Novack DV, Ross FP, Teitelbaum SL. M- CSF mediates TNF-induced inflammatory osteolysis J Clin Invest 2005; 115 : 3418-27. J Oral Pathol Med Liu B 32 367 2003 Liu B, Yu SF, Li TJ. Multinucleated giant cells in various forms of giant cell containing lesions of the jaws express features of osteoclasts J Oral Pathol Med 2003; 32 : 367-75.